Serine-129 phosphorylation of α-synuclein is an activity-dependent trigger for physiologic protein-protein interactions and synaptic function

Output Details

Preprint January 18, 2023

Published December 20, 2023

Phosphorylation of α-synuclein at the serine-129 site (α-syn Ser129P) is an established pathologic hallmark of synucleinopathies and a therapeutic target. In physiologic states, only a fraction of α-syn is phosphorylated at this site, and most studies have focused on the pathologic roles of this post-translational modification. We found that unlike wild-type (WT) α-syn, which is widely expressed throughout the brain, the overall pattern of α-syn Ser129P is restricted, suggesting intrinsic regulation. Surprisingly, preventing Ser129P blocked activity-dependent synaptic attenuation by α-syn—thought to reflect its normal function. Exploring mechanisms, we found that neuronal activity augments Ser129P, which is a trigger for protein-protein interactions that are necessary for mediating α-syn function at the synapse. AlphaFold2-driven modeling and membrane-binding simulations suggest a scenario where Ser129P induces conformational changes that facilitate interactions with binding partners. Our experiments offer a new conceptual platform for investigating the role of Ser129 in synucleinopathies, with implications for drug development.
Tags
  • Alpha-synuclein
  • Original Research
  • Phosphorylation
  • Protein-protein interaction
  • Synapse

Meet the Authors

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    Leonardo Parra-Rivas

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    Kayalvizhi Madhivanan

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    Brent Aulston

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    Lina Wang

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    Dube Dheeraj Prakashchand

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    Nicholas Boyer

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    Veronica Saia-Cereda

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    Kristen Branes-Guerrero

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    Donald Pizzo

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    Pritha Bagchi

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    V.S. Sundar

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    Yong Tang

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    Utpal Das

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    David Scott

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    Padmini Rangamani

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    Yuki Ogawa

  • Subhojit Roy, MD, PhD

    Collaborating PI: Team Gradinaru

    University of California, San Diego