LRRK2 kinase inhibition reverses G2019S mutation-dependent effects on tau pathology spread

Output Details

Preprint October 25, 2023

Published October 6, 2023

Mutations in leucine-rich repeat kinase 2 (LRRK2) are the most common cause of familial Parkinson’s disease (PD). These mutations elevate the LRRK2 kinase activity, making LRRK2 kinase inhibitors an attractive therapeutic. LRRK2 kinase activity has been consistently linked to specific cell signaling pathways, mostly related to organelle trafficking and homeostasis, but its relationship to PD pathogenesis has been more difficult to define. LRRK2-PD patients consistently present with loss of dopaminergic neurons in the substantia nigra but show variable development of Lewy body or tau tangle pathology. Animal models carrying LRRK2 mutations do not develop robust PD-related phenotypes spontaneously, hampering the assessment of the efficacy of LRRK2 inhibitors against disease processes. We hypothesized that mutations in LRRK2 may not be directly related to a single disease pathway, but instead may elevate the susceptibility to multiple disease processes, depending on the disease trigger. To test this hypothesis, we have previously evaluated progression of α-synuclein and tau pathologies following injection of proteopathic seeds. We demonstrated that transgenic mice overexpressing mutant LRRK2 show alterations in the brain-wide progression of pathology, especially at older ages.
Tags
  • LRRK2
  • LRRK2 pathway
  • Original Research
  • PET (Positron emission tomography)
  • Phosphorylated tau
  • Transgenic model

Meet the Authors

  • Danielle (Dani) Bassett, PhD

    Collaborating PI: Team Biederer

    University of Pennsylvania

  • Michael Henderson, PhD

    Co-PI (Core Leadership): Team Biederer Team Lee

    Van Andel Institute

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    Noah Lubben

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    J Kate Brynildsen, PhD

    Key Personnel: Team Biederer

    University of Pennsylvania

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    Connor M. Webb

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    Howard L. Li

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    Cheryl E. G. Leyns

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    Lakshmi Changolkar

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    Bin Zhang

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    Emily S. Meymand

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    Mia O’Reilly

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    Zach Madaj

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    Daniella DeWeerd

    Key Personnel: Team Biederer

    Van Andel Institute

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    Matthew J. Fell

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    Virginia M.Y. Lee